Abstract: Eccrine angiomatous hamartoma (EAH) rarely presents with multiple lesions. Foreign literature has reported cases where the lesions are distributed in a linear, clustered pattern or along the Blaschko's lines, while there is no similar report in China yet. Here, we report on case in this paper. A 26-year-old male presented with linearly distributed purpuric papules, nodules, and plaques accompanied by pruritus on the posteromedial aspect of the right lower extremity for 10 years. He had been diagnosed with lichen planus in multiple other hospitals and received oral and topical medications, but there was no significant improvement. Histopathological examination showed hyperplasia and dilation of eccrine glands and surrounding blood vessels in the middle and lower dermis. The diagnosis of eccrine angiomatous hamartoma was made. The patient was given symptomatic and supportive treatments such as oral antihistamines and topical halometasone cream, and is currently under follow-up.

Key words: linear lesions, hamartoma, eccrine glands, angioma